The UMD-THAP1 mutations database
Record ID: 74

Mutation description


Variation name (cDNA level)Variation name (protein level)Variation statusVariation class
c.135_139delinsGGGTTTAHeterozygousMutation

wt codonwt aamutant codonmutant aamutational eventmutation type
TTTPheindelsindelsindelsindels

StructureKey Residue (HCD)Pyrimidin doubletCpG
L3-THAP dom. DNA binding -

Mutation impact


At the mRNA levelOn restriction map
NANew restriction site(s): none
Lost restriction site(s): none

Conservation (0-1)SIFT (0-1)UMD-predictor (0-100)
0.79 - 65 (Probably pathogenous)

Patient and sample data


Sample IDPatient IDFamily IDPatient statusGenderTransmissionGeographic origin
USA01NYO F0002 I0002502Family WRelativeMaleFamilialAMISH-MENNONITE

Phenotypic groupDisease
Reduced nuclear importSegmental dystonia

Clinical data


SymptomSeverityAge
Age at last examination13
Age of onsetarm9
Arm9
Cranial13
Larynx13
Leg13
Neck13
Speech13
Tongue13
Trunk13

Comments


Reduced nuclear import demonstrated in ref 33.

Reference


Reference IDPubMed IDReference
119182804
Fuchs T, Gavarini S, Saunders-Pullman R, Raymond D, Ehrlich ME, Bressman SB, Ozelius LJ. Mutations in the THAP1 gene are responsible for DYT6 primary torsion dystonia. Nat Genet. 2009 Mar;41(3):286-8.