The UMD-FBN1 mutations database
Record ID: 636

Mutation description


Variation name (cDNA level)Variation name (protein level)Variation statusVariation class
c.6451T>Cp.Cys2151ArgHeterozygousMutation

wt codonwt aamutant codonmutant aamutational eventmutation type
TGCCysCGCArgT->CTs

StructureKey Residue (HCD)Pyrimidin doubletCpG
cb EGF-like #32 Disulfide bonds 2137-2151 (C4)Yes, coding strandNo

Mutation impact


At the mRNA levelOn restriction map
NANew restriction site(s): BstU I
Lost restriction site(s): none

Conservation (0-1)SIFT (0-1)UMD-predictor (0-100)
0.830.00 (pathogenous)100 (Pathogenous)

Patient and sample data


Sample IDPatient statusGenderTransmissionAge of onsetAge of deathGeographic origin
FRA01BOU F0191 I0230ProbandMalefamilialFRANCE

Phenotypic groupDisease
NAClassical MFS

Clinical data


SymptomSeverity
C-Asc. aortic dilatation
C-Mitral valve prolapse
O-Ectopia lentis
O-Flat cornea (<42 dp) (m)
O-Increased axial length of globe (m)
S-Arachnodactyly (M)
S-Arm span/height >1.05 (M)
S-Crowding teeth (m)
S-Dolichostenomelia
S-High arched palate
S-Joint hypermobility (m)
S-Protusio acetabulæ (M)(2)bilateral
S-Scoliosis > 20° (M)(1)severe

Reference


Reference IDPubMed IDReference
6412938084
Collod-B*roud G, Le Bourdelles S, Ades L, Ala-Kokko L, Booms P, Boxer M, Child A, Comeglio P, De Paepe A, Hyland JC, Holman K, Kaitila I, Loeys B, Matyas G, Nuytinck L, Peltonen L, Rantamaki T, Robinson P, Steinmann B, Junien C, B*roud C, Boileau C. "Update of the UMD-FBN1 mutation database and creation of an FBN1 polymorphism database". Hum Mutat. 2003 Sep;22(3):199-208.