The UMD-FBN1 mutations database
Record ID: 579

Mutation description


Variation name (cDNA level)Variation name (protein level)Variation statusVariation class
c.656delAp.His219ProfsX111HeterozygousMutation

wt codonwt aamutant codonmutant aamutational eventmutation type
CACHisdel1bFs.Stop at 329Fr.

StructureKey Residue (HCD)Pyrimidin doubletCpG
Hybrid module#01 Yes, coding strand

Mutation impact


At the mRNA levelOn restriction map
No mechanism suspectedNew restriction site(s): Rma I
Lost restriction site(s): none

Patient and sample data


Sample IDPatient statusGenderTransmissionAge of onsetAge of deathGeographic origin
USA03STA F0067 I807ProbandNAde novo? (50 years old)U.S.A

Phenotypic groupDisease
Type IClassical MFS

Clinical data


Symptom
C-Aortic surgery
C-Asc. aortic dilatation
C-Mitral regurgitation
O-Myopia
S-Arachnodactyly (M)
S-Crowding teeth (m)
S-Dolichostenomelia
S-High arched palate
S-Joint hypermobility (m)
S-Joint limitations
S-Pectus carinatum (M)(2)
S-Scoliosis > 20° (M)(1)
SI-Inguinal hernia
SI-Significant striae atrophicae (m)(1)

Reference


Reference IDPubMed IDReference
10412068374
Schrijver I, Liu W, Odom R, Brenn T, Oefner P, Furthmayr H, Francke U. "Premature termination mutations in FBN1: Distinct effects on Differencial allelic expression and on protein and clinical phenotypes". Am J Hum Genet, 2002, 71: 223-237.