The UMD-FBN1 mutations database
Record ID: 556

Mutation description


Variation name (cDNA level)Variation name (protein level)Variation statusVariation class
c.165_247delp.Pro56HisfsX45HeterozygousMutation

wt codonwt aamutant codonmutant aamutational eventmutation type
GGAGlydel83cFs.Stop at 100Fr.

StructureKey Residue (HCD)Pyrimidin doubletCpG
4-cys motif LTBP-like 4-cysteine motif

Mutation impact


At the mRNA levelOn restriction map
No mechanism suspectedNew restriction site(s): none
Lost restriction site(s): none

Patient and sample data


Sample IDPatient statusGenderTransmissionAge of onsetAge of deathGeographic origin
BEL01GHE F0016 I2089ProbandMalefamilial52 years oldBELGIUM

Phenotypic groupDisease
NAClassical MFS

Clinical data


Symptom
C-Asc. aortic dissection
O-Glaucoma
O-Myopia
S-Arachnodactyly (M)
S-Arm span/height >1.05 (M)
S-Chest deformity (unspecified)
S-Joint hypermobility (m)
SI-Other herniae
SI-Significant striae atrophicae (m)(1)

Reference


Reference IDPubMed IDReference
8911700157
Loeys B, Nuytinck L, Delvaux I, De Bie S, De Paepe A. "Genotype and phenotype analysis of 171 patients referred for molecular study of the fibrillin-1 gene FBN1 because of suspected Marfan syndrome". Arch Intern Med. 2001 Nov 12;161(20):2447-54.