The UMD-FBN1 mutations database
Record ID: 439

Mutation description


Variation name (cDNA level)Variation name (protein level)Variation statusVariation class
c.IVS16-1G>C (c.2114-1G>C)HeterozygousMutation

wt codonwt aamutant codonmutant aamutational eventmutation type
GCGAlaspl-1Spl.G->CTv

StructureKey Residue (HCD)Pyrimidin doubletCpG
TGFBP#02 

Mutation impact


At the mRNA levelOn restriction map
Skipping of exon 17, in frameNew restriction site(s): none
Lost restriction site(s): none

Impact on splicing
Splice site type Wild type sequence CV Mutant type sequence CV Variation (%)
Acceptor
aatttattgcagCG
83.5 _
aatttattgcacCG
54.6 _ *
-34.7 %

Patient and sample data


Sample IDPatient statusGenderTransmissionAge of onsetAge of deathGeographic origin
BEL01GHE F0065 I0795ProbandFemalede novo4 years oldBELGIUM

Phenotypic groupDisease
NAClassical MFS

Clinical data


Symptom
C-Asc. aortic dilatation
C-Mitral valve prolapse
C-Pulmonary art. dilatation
O-Ectopia lentis
S-Arachnodactyly (M)
S-Protusio acetabulæ (M)(2)
S-Reduced US/LS ratio <0.87 (M)
S-Scoliosis > 20° (M)(1)

Reference


Reference IDPubMed IDReference
8911700157
Loeys B, Nuytinck L, Delvaux I, De Bie S, De Paepe A. "Genotype and phenotype analysis of 171 patients referred for molecular study of the fibrillin-1 gene FBN1 because of suspected Marfan syndrome". Arch Intern Med. 2001 Nov 12;161(20):2447-54.