The UMD-FBN1 mutations database
Record ID: 425

Mutation description


Variation name (cDNA level)Variation name (protein level)Variation statusVariation class
c.5076_5082delp.Arg1692SerfsX21HeterozygousMutation

wt codonwt aamutant codonmutant aamutational eventmutation type
AGAArgdel7cFs.Stop at 1712Fr.

StructureKey Residue (HCD)Pyrimidin doubletCpG
TGFBP#05 

Mutation impact


At the mRNA levelOn restriction map
No mechanism suspectedNew restriction site(s): none
Lost restriction site(s): none

Patient and sample data


Sample IDPatient statusGenderTransmissionAge of onsetAge of deathGeographic origin
ITA01FLO F0007 I04ProbandFemalefamilial29 years oldITALIA

Phenotypic groupDisease
NAClassical MFS

Clinical data


Symptom
C-Mitral regurgitation
C-Mitral regurgitation
CNS-Lumbosacral dural ectasia
L-Spontaneous pneumothorax
O-Myopia
S-Arachnodactyly (M)
S-Chest deformity (unspecified)
S-Crowding teeth (m)
S-High arched palate
S-Joint dislocation
S-Joint hypermobility (m)
S-Reduced US/LS ratio <0.87 (M)
S-Scoliosis > 20° (M)(1)
SI-Significant striae atrophicae (m)(1)

Reference


Reference IDPubMed IDReference
9311453977
Pepe G, Giusti B, Evangelisti L, Porciani MC, Brunelli T, Giurlani L, Attanasio M, Fattori R, Bagni C, Comeglio P, Abbate R, Gensini GF. "Fibrillin-1 (FBN1) gene frameshift mutations in Marfan patients: genotype-phenotype correlation". Clin Genet. 2001 Jun;59(6):444-50.