The UMD-FBN1 mutations database
Record ID: 2189

Mutation description


Variation name (cDNA level)Variation name (protein level)Variation statusVariation class
c.4729T>Gp.Cys1577GlyHeterozygousMutation

wt codonwt aamutant codonmutant aamutational eventmutation type
TGTCysGGTGlyT->GTv

StructureKey Residue (HCD)Pyrimidin doubletCpG
TGFBP#04 C in disulfide bonds 1563-1577NoNo

Mutation impact


At the mRNA levelOn restriction map
NANew restriction site(s): Ava II, EcoO109 I, Nla IV, PpuM I
Lost restriction site(s): none

Conservation (0-1)SIFT (0-1)UMD-predictor (0-100)
10.00 (pathogenous)100 (Pathogenous)

Patient and sample data


Sample IDPatient statusGenderTransmissionAge of onsetAge of deathGeographic origin
USA01BAL F0039 I0001ProbandMalefamilialU.S.A.

Phenotypic groupDisease
NAStiff Skin Syndrome

Clinical data


SymptomSeverityAge
O-Myopia54
OS-Neuropathy54
S-Camptodactyly54
S-Joint limitationselbow, shoulder, knee54
SI-MCP/IP nodules54
SI-Stiff skin54

Reference


Reference IDPubMed IDReference
20620375004
Loeys, B. L., Gerber, E. E., Riegert-Johnson, D., Iqbal, S., Whiteman, P., McConnell, V., Chillakuri, C. R., Macaya, D., Coucke, P. J., De Paepe, A., Judge, D. P., Wigley, F., Davis, E. C., Mardon, H. J., Handford, P., Keene, D. R., Sakai, L. Y., Dietz, H. C. "Mutations in fibrillin-1 cause congenital scleroderma: stiff skin syndrome". Sci. Transl. Med. 2010, 2: 23ra20.