The UMD-FBN1 mutations database
Record ID: 1883

Mutation description


Variation name (cDNA level)Variation name (protein level)Variation statusVariation class
c.3256T>Cp.Cys1086ArgHeterozygousMutation

wt codonwt aamutant codonmutant aamutational eventmutation type
TGTCysCGTArgT->CTs

StructureKey Residue (HCD)Pyrimidin doubletCpG
cb EGF-like #12 Disulfide bonds 1074-1086 (C3)NoNo

Mutation impact


At the mRNA levelOn restriction map
NANew restriction site(s): none
Lost restriction site(s): none

Conservation (0-1)SIFT (0-1)UMD-predictor (0-100)
0.830.00 (pathogenous)100 (Pathogenous)

Patient and sample data


Sample IDPatient statusGenderTransmissionAge of onsetAge of deathGeographic origin
USA14ALL F0001 I0001ProbandMalede novoat birth4 daysU.S.A.

Phenotypic groupDisease
NANeonatal MFS

Clinical data


SymptomSeverity
C-Asc. aortic dilatation
C-Mitral regurgitationmoderate
CF-Broad nasal bridge
CF-Dolichocephaly
S-Abnormal ears
S-Arachnodactyly (M)
S-High arched palate
S-Joint limitations
S-Muscular hypotonia
S-Plain pes planus (M)(1)
SI-Loose, redundant skin

Reference


Reference IDPubMed IDReference
17018377451
Sutherell J, Zarate Y, Tinkle BT, Markham LW, Cripe LH, Hyland JC, Witte D, Hopkin RJ, Hinton RB. "Novel fibrillin 1 mutation in a case of neonatal Marfan syndrome: the increasing importance of early recognition". Congenit Heart Dis. 2007 Sep;2(5):342-6