The UMD-FBN1 mutations database
Record ID: 17

Mutation description


Variation name (cDNA level)Variation name (protein level)Variation statusVariation class
c.3220T>Cp.Cys1074ArgHeterozygousMutation

wt codonwt aamutant codonmutant aamutational eventmutation type
TGCCysCGCArgT->CTs

StructureKey Residue (HCD)Pyrimidin doubletCpG
cb EGF-like #12 Disulfide bonds 1074-1086 (C1)NoNo

Mutation impact


At the mRNA levelOn restriction map
NANew restriction site(s): none
Lost restriction site(s): none

Conservation (0-1)SIFT (0-1)UMD-predictor (0-100)
0.830.00 (pathogenous)100 (Pathogenous)

Patient and sample data


Sample IDPatient statusGenderTransmissionAge of onsetAge of deathGeographic origin
FIN01HEL F0003 I01ProbandNAde novoat birth9,5 weeks FINLAND

Phenotypic groupDisease
ECM incorporationNeonatal MFS

Clinical data


Symptom
C-Asc. aortic dilatation
C-Congestive heart failure
C-Mitral regurgitation
C-Mitral valve prolapse
O-Microphthalmus
S-Abnormal ears
S-Arachnodactyly (M)
S-Characteristic facial appearance
S-Dolichostenomelia
S-Joint hypermobility (m)
S-Joint limitations
S-Pectus carinatum (M)(2)
SI-Loose, redundant skin

Reference


Reference IDPubMed IDReference
108136837
Kainulainen K, Karttunen L, Puhakka L, Sakai L, Peltonen L. "Mutations in the fibrillin gene responsible for dominant ectopia lentis and neonatal Marfan syndrome". Nat Genet 1994 Jan;6(1):64-9.